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Received : 30-08-2023

Accepted : 27-09-2023



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Get Permission Lakshmi, Rao, Lakshmi, Jhansi, and Aliveni: Chronic tophaceous gout – A case report


Introduction

Gouty arthritis is a condition that presents with devitalizing clinical symptoms and impaired functionality, all which have a significant impact on the quality of life. Initially triggered by the deposition of monosodium urate crystals into the joint space, it results in an inflammatory cascade causing the secretion of several proinflammatory cytokines and neutrophil recruitment into the joint.1 Normal uric acid levels are between 3.5 to 7.2 mg/dl in adult males and postmenopausal women and between 2.6 to 6.0mg/dl in premenopausal women.2 However uric acid level of greater than 6.8mg/dl, also known as hyperuricemia, is the key risk factor for gout.3, 4 While it is generally asymptomatic, when the concentration of uric acid exceeds the body threshold, monosodium urate crystals precipitate in the cooler areas of the body which leads to gout.5 The presentation of gout varies from an acute arthritis manifesting as severe pain and inflammation around the affected joint to a chronic presentation as deposition of uric acid crystals in the joint called tophi. Clinical features of gout include sudden onset arthritis, excruciating joint pain, hyperaemia and rise in local temperature around the involved joint. Pharmacological therapies include uricosuric drugs (eg. Probenicid), xanthine oxidase inhibitors (eg. Allopurinol), urate oxidases (eg. Uricases), NSAIDS, and colchicine. Non pharmacological therapies include life style changes and dietary changes.6

Case Report

A 60 years old male patient came with a complaint of swelling at posterior aspect of left elbow joint since 2 years and pain since 15 days. He was a smoker, alcoholic and takes non-vegetarian diet. There is no significant personal, past and family history.

On physical examination, there was a tender swelling noted on the left elbow joint measuring 3.5 x 1.5 x 1cm. Other non tender swellings noted on bilateral first tarso-metatarsal, knee, and right elbow joints. All the swellings are firm in consistency and showed restricted mobility. Clinically the case was diagnosed as Olecranon bursitis and further investigations were done. (Figure 1)

Figure 1

Clinical images of the swellings in different joints

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On investigation, Hemoglobin is 9.4 gm/dl, ESR: 80mm/1st hr. Renal function tests showed increased uric acid – 8.6 gm/dl. Ultrasound abdomen showed bilateral Grade 1 Renal parenchymal changes. Intra operatively calcifications were noted over the soft tissue mass and triceps tendon. The mass over triceps tendon was excised and sent for histopathological examination.

On gross examination, we received a fibrofatty mass measuring 3.5 x 1.5 x 1cm. (Figure 2)

Cut section showed white flakes (? Calcifications). (Figure 3)

Figure 2

Excised swelling from elbow measuring 3.5 x 1.5 x 1cm

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Figure 3

Cut-section showing small spaces with calcified areas

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Microscopy

Out of our curiosity, we immediately made a wet film and a crush smear from white flakes. Wet film (Figure 4) and crush smear (Figure 5) showed needle shaped crystals.

Figure 4

Photomicrograph of wet saline mount showing needle shaped crystals. (10X)

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Figure 5

Photomicrograph of crush smear showing needle shaped crystals (Giemsa, 10X)

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Hematoxylin and eosin sections showed fibrocollagenous tissue with several tophi made up of pink eosinophilic material surrounded by foreign body giant cell reaction and lymphocytes. There are several cystic spaces filled with calcareous debris. (Figure 6)

Figure 6

Photomicrograph shows several tophi (H&E,10X)

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Figure 7

Photomicrograph shows Tophi made up of pink eosinophilic material (H&E,40X)

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Discussion

A tophus is accumulation of large amounts of uric acid crystals in chronic untreated gout. This progresses into destruction of joints with formation of palpable tophi. Tophi leads to joint destruction and deformity.7 Formation of tophi is the cardinal feature of advanced gout. Microscopically, tophi are foreign body granuloma-like structures containing collections of monosodium urate (MSU) crystals surrounded by inflammatory cells and connective tissue.8

In patients with hyperuricemia, the monosodium urate crystals may get deposited in the joints leading to gouty arthritis. This MSU-induced inflammation is driven by components of the innate immune system.9

The inflammatory response in the gouty arthritis begins with phagocytosis of MSU crystals by macrophages. This triggers the formation of a protein scaffold known as an inflammasome within the cytosol of the macrophage. The inflammasome helps in activation of pro-IL-1β, which is then secreted from the cell when there is co-stimulation with free fatty acids or lipopolysaccharide.10, 11 So after a large meal or alcohol consumption, there is increase in free fatty acid concentrations in the blood, triggering release of IL-1β, which plays a key role in the development of gouty arthritis flares.11

IL-1β regulates cell proliferation, differentiation, and apoptosis. IL-1β also activates IL-1 receptor on endothelial cells which facilitates the transcription of proinflammatory cytokines and chemokines that drive subsequent inflammatory processes.10, 12 This causes neutrophil influx to the synovium which results in further phagocytosis of MSU crystals, IL-1β release and its associated inflammatory processes.13 The acute inflammation and repeated flares of gouty arthritis result in pathological joint destruction. Prolonged accumulation of MSU crystals gives rise to tophi which on microscopy show crystals in a matrix of lipids, protein, and mucopolysaccharides.14 IL-1 is a key molecule in the process of bone and cartilage damage and plays a critical role in osteoclast formation.14

Conclusion

Gout is an avoidable complication of hyperuricemia. This patient was unaware of his disease and presented with chronic tophi for which he had to undergo excision procedures. So educating the patients about the disease, changes in lifestyle such as weight loss in obese individuals, dietary changes to reduce purine intake particularly non vegetarian diet, reduce alcohol consumption and sweetened beverages, and regular exercises to prevent progression and importance of follow-up can decrease morbidity and financial burden on the patient.

Source of Funding

None.

Conflict of Interest

None.

References

1 

EB Gonzalez An update on the pathology and clinical management of gouty arthritisClin Rheumatol20123111321

2 

G Desideri G Castaldo A Lombardi M Mussap A Testa R Pontremoli Is it time to revise the normal range of serum uric acid levels?Eur Rev Med Pharmacol Sci20141891295306

3 

RK Narang N Dalbeth Pathophysiology of GoutSemin Nephrol202040655063

4 

S Sinha R Rijal J Shah P Chaudhary A Case of Surgically Intervened Chronic Tophaceous Gout and Review of LiteratureJ Orthop Case Rep2019101669

5 

G Ragab M Elshahaly T Bardin Gout: An old disease in new perspective - A reviewJ Adv Res20178549511

6 

V Kumar AK Abbas JC Aster JA Perkins Robbins & Cotran Pathologic Basis of Disease10th EdElsevierNetherlands2018

7 

A Chhana N Dalbeth The gouty tophus: a reviewCurr Rheumatol Rep201517319

8 

Y Shi JE Evans KL Rock Molecular identification of a danger signal that alerts the immune system to dying cellsNature2003425695751621

9 

F Martinon V Pétrilli A Mayor A Tardivel J Tschopp Gout-associated uric acid crystals activate the NALP3 inflammasomeNature2006440708123741

10 

LAB Joosten MG Netea E Mylona MI Koenders RKS Malireddi M Oosting Engagement of fatty acids with Toll-like receptor 2 drives interleukin-1β production via the ASC/caspase 1 pathway in monosodium urate monohydrate crystal-induced gouty arthritisArthritis Rheum20106211323748

11 

RM Pope J Tschopp The role of interleukin-1 and the inflammasome in gout: implications for therapyArthritis Rheum2007561031838

12 

N Schlesinger RG Thiele The pathogenesis of bone erosions in gouty arthritisAnn Rheum Dis [Internet]20106911190712

13 

R Torres L Macdonald SD Croll J Reinhardt A Dore S Stevens Hyperalgesia, synovitis and multiple biomarkers of inflammation are suppressed by interleukin 1 inhibition in a novel animal model of gouty arthritisAnn Rheum Dis2009681016028

14 

J Werina K Redlich K Polzer TNF-induced structural joint damage is mediated by IL-1Proc Natl Acad Sci200710428117427



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